DOI: https://doi.org/10.36347/sasjs.2026.v12i05.003

Pages: 351-353

Introduction: Urethral duplication is a rare congenital anomaly with diverse presentations. Prepubic sinus is considered a variant, possibly representing incomplete dorsal urethral duplication. Case presentation: A 14-month-old boy presented with a dorsal penile opening associated with intermittent purulent and urine-like discharge. Imaging demonstrated a sinus tract extending toward the pubic symphysis without communication with the native urethra. Surgical excision of the tract was performed. Histopathology revealed a tract lined by both stratified squamous epithelium and urothelium. Discussion: The presence of urothelial lining supports the diagnosis of urethral duplication rather than a simple dermoid or epidermoid sinus. Complete excision is curative. Conclusion: Prepubic sinus should be considered a variant of dorsal urethral duplication. Accurate diagnosis requires imaging and histopathology, and surgical excision yields excellent outcomes.